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Case Reports
. 2014 Jul-Dec;4(2):230-3.
doi: 10.4103/2231-0746.147158.

A rare cause of lateral facial swelling

Affiliations
Case Reports

A rare cause of lateral facial swelling

Sujata Mohanty et al. Ann Maxillofac Surg. 2014 Jul-Dec.

Abstract

A case of chronic, recurrent and asymptomatic facial swelling in a young male is presented. Swelling extended from lower midface to upper lateral neck and right commissure to anterior massetric border. History, clinical signs and symptoms and examination pointed towards the benign nature of the swelling. Fine-needle aspiration cytology tapered the diagnostic possibilities to a salivary cyst or pseudocyst. Ultrasonography identified the lesion to contain echogenic fluid with irregular borders. "Tail sign" was absent on contrast magnetic resonance imaging, excluding the involvement of the sublingual gland. Surgical excision of the lesion was done along with submandibular gland as both were in continuity via a bottle-neck tract. Final histopathological diagnosis was that of the submandibular gland extravasation phenomenon. As per the best of our knowledge, it is the first case report of a submandibular gland extravasation causing swelling in a retrograde direction onto the face.

Keywords: Extravasation phenomenon; pseudocyst; submandibular gland; tail sign.

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Conflict of interest statement

Conflict of Interest: None declared.

Figures

Figure 1
Figure 1
Preoperative presentation of patient showing facial extension of submandibular swelling
Figure 2
Figure 2
(a) T1-weighted (T1W) axial magnetic resonance imaging (MRI) showing a well marginated lesion in the right submandibular region. The lesion shows a hypointense signal with no septations. (b) Fat suppressed T2W axial MRI showing the lesion to be high signal. The compressed submandibular gland is seen lying adjacent to the lesion. (c) Fat suppressed T2W axial MRI showing the lesion to have a small projection towards the floor of the mouth. The typical “tail sign” of a plunging ranula was not seen. (d) Post-contrast axial MRI showing the lesion having a thin peripheral rim enhancement
Figure 3
Figure 3
Exposure via submandibular approach
Figure 4
Figure 4
Facial extension of lesion dissected (circled) and found to be in continuity with submandibular gland
Figure 5
Figure 5
Resected lesion and submandibular gland
Figure 6
Figure 6
(a) Superficial infiltration of chronic inflammatory cells admixed within loosely textured collagen fibers (H and E, ×100). (b) Loosely textured collagen fibers with numerous mucinophages (PAS, ×400)
Figure 7
Figure 7
Six months postoperative photograph

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