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Case Reports
. 2020 Nov 2;13(11):e238485.
doi: 10.1136/bcr-2020-238485.

Treatment of tongue telangiectasia in a patient with hereditary haemorrhagic telangiectasia

Affiliations
Case Reports

Treatment of tongue telangiectasia in a patient with hereditary haemorrhagic telangiectasia

Eve Mandisa Rader Bowers et al. BMJ Case Rep. .

Abstract

A 61-year-old Caucasian woman presented to an outpatient otolaryngology clinic with increased bleeding from a dorsal tongue telangiectasia for 3 weeks. Her history was significant for hereditary haemorrhagic telangiectasia (HHT), a rare condition that causes vascular dysplasia, and recent symptomatic anaemia requiring blood transfusions. After failing medical management with topical haemostatic agents, she was offered and underwent surgical intervention to remove the tongue telangiectasia with duel therapy potassium titanyl phosphate (KTP) laser coblation and bevacizumab injections. A team of otolaryngologists removed the lesion without complications, and the patient denied bleeding, had minimal pain, and endorsed increased quality of life postoperatively. Tongue telangiectasias can cause life-threatening bleeding in some patients with HHT, and no surgical management guidelines exist to treat them. This case demonstrates the efficacy of KTP laser followed by bevacizumab injections in treating tongue telangiectasias in a patient with HHT.

Keywords: ear; head and neck surgery; nose and throat; nose and throat/otolaryngology; otolaryngology / ENT; therapeutic indications.

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Conflict of interest statement

Competing interests: None declared.

Figures

Figure 1
Figure 1
Dorsal tongue telangiectasia following potassium titanyl phosphate ablation at a setting of 4 Watts.
Figure 2
Figure 2
Submucosal bevacizumab injections of tongue telangiectasias.

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