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Case Reports
. 2022 Jan 13;15(1):e245424.
doi: 10.1136/bcr-2021-245424.

Opening a dacryocystorhinostomy into the opposite nasal cavity in a case of hemiarhinia

Rachna Meel  1 , Asha Samdani  1 , Sahil Agrawal  1 , Deepsekhar Das  2
Affiliations
Case Reports

Opening a dacryocystorhinostomy into the opposite nasal cavity in a case of hemiarhinia

Rachna Meel et al. BMJ Case Rep. .

Abstract

Heminasal agenesis is an exceedingly rare congenital anomaly which is frequently associated with disorders of eye, lacrimal drainage system and face. At times, a proboscis may also be noted with this condition. Herein, we present a case of a 13-year-old boy who presented to us with heminasal agenesis with concomitant microphthalmos, leucomatous corneal opacity, blepharoptosis, dacryocystocoele and maxillary hypoplasia. The child underwent a modified transeptal external dacryocystorhinostomy with placement of a lacrimal stent. There was significant improvement of epiphora and discharged following surgery. Heminasal aplasia with dacryocystocoele is surgical challenge; however, a well thought out surgical approach can yield satisfactory outcomes.

Keywords: congenital disorders; ear, nose and throat/otolaryngology; ophthalmology.

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Conflict of interest statement

Competing interests: None declared.

Figures

Figure 1
Figure 1
Clinical picture of the patient showing heminasal aplasia, medial canthal dystopia, lacrimal sac mucocoele and ptosis and corneal opacity on the left side. (A) Image from front; (B) Side view from right; (C) Side view from left.
Figure 2
Figure 2
(A, B) CT (coronal cuts) showing obliterated left maxilla sinus and the nasal cavity with a deviated nasal septum directed to the left side, and (axial cuts) (C, D) calcified lens and ocular coat calcification.
Figure 3
Figure 3
Postoperative 2 weeks follow-up of the patient with decreased tearing and absent medial canthal swelling.
See this image and copyright information in PMC

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