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Review
. 2021 Oct-Dec;62(4):1045-1050.
doi: 10.47162/RJME.62.4.17.

Unilateral agenesis of permanent superior canine in familial peg-shaped lateral incisors: rare case report and literature review

Oana Cella Andrei  1 , Cătălina Farcaşiu, Adriana Bisoc, Daniela Ioana Tărlungeanu, Livia Alice Tănăsescu, Magdalena Natalia Dina, Mihai Burlibaşa, Ruxandra Mărgărit
Affiliations
Review

Unilateral agenesis of permanent superior canine in familial peg-shaped lateral incisors: rare case report and literature review

Oana Cella Andrei et al. Rom J Morphol Embryol. 2021 Oct-Dec.

Abstract

Agenesis of permanent maxillary and mandibular canines is very rare; one to all four can be missing, isolated or in association with other missing teeth or with dental morphology abnormalities. Such cases can present functional, esthetic, and psychological problems, since the canine's role in functional occlusion and in obtaining an aesthetic smile is crucial. Frequently, the canine's absence from the arch is caused by impaction; its congenital absence is extremely rare in patients with no associated syndrome. The aim of this paper was to present a very rare case of a non-syndromic Romanian adult female patient with a unilateral permanent maxillary missing canine, in association with peg-shaped maxillary lateral permanent incisors, which can have a genetic cause, since the same morphological abnormality was present in her father and her younger sister, who also presented a rare situation of bilateral upper transposition between the canines and lateral incisors. The association of a permanent maxillary canine hypodontia with bilateral "peg laterals" and transposition between the maxillary canine and the peg-shaped lateral incisors is also rare as a family character in healthy patients. Future statistical studies are necessary to establish the incidence of permanent maxillary canine agenesis in Romanian population. Also, the article includes a detailed literature review of reported cases of agenesis of permanent maxillary canines.

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Conflict of interest statement

The authors declare that they have no conflict of interests.

Figures

Figure 1
Figure 1
(a and b) Aspect of the mandibular arch at presentation; aspect of peg-shaped maxillary lateral incisors, persistence of the primary maxillary left superior canine
Figure 2
Figure 2
(a and b) Panoramic radiological investigation showing the absence of the permanent maxillary left canine; retroalveolar radiograph showing the minimal degree of the root resorption of the persistent primary canine
Figure 3
Figure 3
(a–c) Present clinical situation of the second patient: diagnostic cast of the maxillary arch, diagnostic cast of the mandibular arch and occlusion, showing the pronounced abrasion of the remaining maxillary teeth
Figure 4
Figure 4
(a and b) Old photography of the father showing peg-shaped maxillary lateral incisors and the presence of both permanent canines; similar shape and aspect of the first patient’s permanent canine and incisors
Figure 5
Figure 5
Panoramic radiological investigation showing the third patient’s peg-shaped maxillary lateral incisors and the presence of both permanent canines, having similar shape with her father’s and sister’s
Figure 6
Figure 6
Panoramic radiological investigation of the mother, showing the presence of both permanent maxillary canines and no similarity in incisor’s or canine’s shape
See this image and copyright information in PMC

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