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. 2021 Aug 5;14(2):9270.
doi: 10.4081/dr.2021.9270. eCollection 2022 Jun 16.

Unilateral Morbihan syndrome

Laura Macca  1 , Federica Li Pomi  1 , Alfonso Motolese  1 , Paolo Broganelli  2 , Francesco Borgia  1
Affiliations

Unilateral Morbihan syndrome

Laura Macca et al. Dermatol Reports. .

Abstract

Morbihan Syndrome is an uncommon condition characterized by the slow appearance of erythema and solid edema on the upper portion of the face. The disease is considered an end-stage complication of rosacea's recurrent episodes of vascular dilation and inflammation or a complication of acne vulgaris. The disease is often insidious to diagnose and challenging to treat. We report a paradigmatic case of unilateral Morbihan Syndrome induced by use of fullface CPAP masks for OSAS in a patient with rosacea. OSAS could play a role in the development of rosacea symptoms. Our aim is to remark the importance of a careful, prolonged follow-up to optimize patient's management and to improve the adherence to therapy.

Keywords: Continuous positive airway pressure; Morbihan disease; Obstructive sleep apnea; Rosacea; Solid persistent facial edema.

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Conflict of interest statement

Conflict of interest: The authors declare no potential conflict of interest.

Figures

Figure 1.
Figure 1.
Frontal and side view of the face before starting treatment. Severe nondepressive solid edema of the right lid, partially involving the glabella and the dorsa of the nose.
Figure 2.
Figure 2.
Frontal and side view of the face after six months of treatment with oral isotretinoin.
See this image and copyright information in PMC

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