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Case Reports
. 2022 Oct;37(10):3432-3435.
doi: 10.1111/jocs.16771. Epub 2022 Jul 21.

Postinflammatory rupture of right coronary artery ostium complicating Behçet disease

Antonio Fiore  1   2 , Mariantonietta Piscitelli  1 , Amel Rabia  1 , Haytham Derbel  3 , Eric Bergoend  1 , Sanjeet S Avtaar Singh  4 , Francesco Nappi  5
Affiliations
Case Reports

Postinflammatory rupture of right coronary artery ostium complicating Behçet disease

Antonio Fiore et al. J Card Surg. 2022 Oct.

Abstract

Introduction: Behçet disease (BD) is a chronic relapsing inflammatory disease of unknown etiology, characterized by variable clinical manifestations.

Methods: A 28-year-old woman with BD Cardiovascular and Bipolar Disorder underwent emergency surgical treatment of ascending aortic pseudoaneurysm for ruptured right coronary ostium.A modified Bentall procedure with tricuspid annuloplasty, surgical thrombectomy, and a single coronary artery bypass using a saphenous vein graft was performed. A biological prosthesis was used initially but subsequently deteriorated. We then successfully performed a valve-in-valve (ViV) transcatheter aortic valve implantation (TAVI).

Results: The postoperative recovery was uneventful and at follow-up, two years post valve procedure, the patient was completely symptom-free. She remains under long-term medical surveillance.

Conclusion: The management of BD with cardiac involvement must be led by a multidisciplinary team.

Keywords: Behçet disease; anticoagulation therapy; bipolar disorder; cardiac reoperation; neurobehavioral; transcatheter aortic valve implantation.

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References

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