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Case Reports
. 2023 Oct:111:108834.
doi: 10.1016/j.ijscr.2023.108834. Epub 2023 Sep 25.

Unilateral complete fibular dimelia and diplopodia: A case report and literature review

Michael Uglow  1 , Tauseef Machhiwala  2 , Amira Babikir  3 , Irshad Waheed  1
Affiliations
Case Reports

Unilateral complete fibular dimelia and diplopodia: A case report and literature review

Michael Uglow et al. Int J Surg Case Rep. 2023 Oct.

Abstract

Introduction and importance: We present a case of Congenital fibular dimelia or fibula duplication with tibial hypoplasia, talar duplication and diplopodia with two complete pre-axial rays. This association has not been published in the literature to our knowledge. We discuss the unique features and surgical management of this rare condition.

Case presentation: The patient is a 3 year old child with congenital unilateral fibular dimelia, tibial hypoplasia, talar duplication and diplopodia who presented to us with leg length discrepancy and progressive equinovarus deformation of the right foot and ankle. She was surgically treated by excision of the medial two rays, cuneiforms, navicular, duplicate talus, os calcis and medial accessory fibula with reconstruction of the ankle joint capsule and foot reconstruction.

Discussion: Due to the rarity of the condition there is no described treatment protocol. It was decided to do resection taking in consideration of the disabling and unsightly progressive deformity.

Conclusion: The case presented is a very rare of type of duplication deformity which we believe to be unique. The surgical treatment has been performed due to progressive deformity based on principles of management. Future follow up to observe growth and development of the lower limb joints, especially the ankle, as well as treatment for leg length equalization will be required.

Keywords: Case report; Diplopodia; Fibular dimelia; Orthopedic; Pre-axial polydactyly; Talar duplication.

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Conflict of interest statement

Declaration of competing interest None.

Figures

Fig. 1
Fig. 1
Right lower limb and 3D.
Fig. 2
Fig. 2
Plain radiographs of bilateral lower limbs showing fibula dimelia on right side.
Fig. 3
Fig. 3
CT angiography of bilaterial lower limb with 3D reconstruction.
Fig. 4
Fig. 4
Intra-op image of surgical specimen.
Fig. 5
Fig. 5
Post operative wound closure.
Fig. 6
Fig. 6
Right leg healed wound 4 months post operative.
Fig. 7
Fig. 7
Post-operative 10 months standing xray.
See this image and copyright information in PMC

References

    1. Negm Y.A.H. Human malformations and related anomalies, second edition. Arch. Dis. Child. 2007;92(3):280.
    1. Kitta M.I., Azis H.S., Santoso N.Y., Iswahyudi Fahlevi R.R., Arden F. Congenital diplopodia-A rare case of duplicated lower limb: a case report. Int J Surg Case Rep. 2021;87 106390. - PMC - PubMed
    1. Khan S.A., Kumar A., Varhney M.K. A rare association of deformities with diplopodia, aplasia of the tibia and double fibula: a case report. J Med Case Reports. 2008;2:102. - PMC - PubMed
    1. Narang I.C., Mysorekar V.R., Mathur B.P. Diplopodia with double fibula and agenesis of tibia – a case report. Bone Joint J. 1982;64:206–209. - PubMed
    1. Bayram H., Herdem M., Temocin A.K. Fibular dimelia and mirror foot without associated anomalies. Clin. Genet. 1996;49:311–313. - PubMed

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